Introduction: Taeniasis is a condition when humans (definitive host) are infected with adult tapeworms in the intestine whereas cysticercosis is infection with larval forms (i.e., Cysticercus cellulosae). Case description: We present a rare case of isolated sternocleidomastoid muscle cysticercosis which was diagnosed with help of USG and treated successfully by pharmacotherapy (albendazole and steroids). Discussion: The cysticercous larva enters the circulatory system by penetrating and crossing the bowl wall. Through blood stream these larvae migrate to sites of lodgement which includes brain (most common), skeletal muscles, eyes, liver and subcutaneous tissues. Conclusion: Isolated muscle involvement is not common and thus often presenting as isolated asymptomatic swelling, it poses challenges in diagnosis.